Author/Authors :
Rezaei Kanavi, Mozhgan Ophthalmic Research Center - Shahid Beheshti University of Medical Sciences, Tehran, Iran , Javadi, Fatemeh Shahed University of Medical Sciences, Tehran, Iran , Javadi, Mohammad-Ali Ophthalmic Research Center - Shahid Beheshti University of Medical Sciences, Tehran, Iran , Faramarzi, Amir Ophthalmic Research Center - Shahid Beheshti University of Medical Sciences, Tehran, Iran
Abstract :
Purpose: To report a rare presentation of unifocal Langerhans cell histiocytosis (LCH)
simulating a limbal papilloma.
Case report: A 24-year-old man presented with a limbal mass in his left eye which
had initially been suspected to be a papilloma based on clinical findings. The mass
was excised and a histopathological diagnosis of “acute bullous inflammation with
granulation tissue” was made. The lesion relapsed 10 months later which necessitated
repeat resection along with corneoscleral patch grafting. Histopathological studies of
the excised lesion led to a final diagnosis of LCH.
Conclusion: To the best of our knowledge, this is the second report of a rare presentation
of LCH in the limbus which recurred after excision of the primary mass. The recurrent
lesion was diagnosed based on histopathology and managed accordingly.
