Management of Psychosis in a Patient withProbable Dopa-Responsive Dystonia

Dopa-responsive dystonia is a rare childhoodneurological disorder characterized by asymmetric dystonia, predominantly of thelower limb, that responds excellently to levodopa replacement therapy. Although it is known that behavioral changes, such asdepression, anxiety disorders, and sleep disturbances, typically follow onset of motor symptoms, there is limited literature on thepsychiatric symptoms of this disorder. This report describes a novel case of a 20-year-old male with a history of dopa-responsivedystonia and schizoaffective disorder who presented with both dystonia and psychosis after a period of medication noncompliance.This case provides a reference for the management of psychosis in patients with dopa-responsive dystonia and highlights the needfor more research on the nonmotor symptoms that accompany this neurological disorder